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Clinical Case Reports, Int’l Journal of
2013, Vol.3, No.17, 76-78
http://ijccr.sophiapublisher.com
Case Report
Open Access
A Case of a Rare Acquired Inflammatory Arterio-venous Malformation with
Spontaneous Resolution
Wong K.B.
1
, Chan S.A.
2
, Abid Q.
1
1. Cardiothoracic Department and Radiology Department, University Hospital of North Staffordshire, UK
2. City Hospital Birmingham, UK
Corresponding Author email: kianboon_w@yahoo.com;
Author
International Journal of Clinical Case Reports, 2013, Vol.3, No.17 doi: 10.5376/ijccr.2013.03.0017
Copyright
© 2013 Wong et al. This is an open access article published under the terms of the Creative Commons Attribution License, which permits unrestricted
use, distribution, and reproduction in any medium, provided the original work is properly cited.
Abstract
There is no single reported case on inflammatory pulmonary arterio-venous malformation (PAVM) which resolves
completely without any intervention. We are the first to report a case in which an inflammatory PAVM achieved complete resolution
without any treatment. A 62 years old gentleman presented with gradual worsening dyspnoea on exertion and haemoptysis after
aspirated oral contrast. On investigation, contrast enhanced computated tomography scan revealed a right lower lobe arterio-venous
malformation. However, after a few months, a follow up CT was performed and it revealed a complete resolution. Conservative
management approach for inflammatory PAVM can be taken at the initial stage because complete resolution is possible in some cases.
However, a close monitoring is required to ensure a complete resolution.
Keywords
Pulmonary arterio-venous malformation; Osler-weber-rendu; CT scan; Inflammatory; Complete resolution
Introduction
A pulmonary arterio-venous malformation (PAVM) is
a rare condition which is predominantly a congenital
malformation known as Osler-Weber-Rendu, also
known as Hereditary Haemorrhagic Telangiectesia
(HHT) (Hayashi et al., 2012). However, there is yet to
be cases on spontaneously resolved acquired
inflammatory AVM being reported in the literature.
We are the first to report an acquired inflammatory
pulmonary AVM which resolved spontaneously
without any medical or surgical treatment.
1 Case
A 62 years old gentleman presented with a few days
history of haemoptysis and increased shortness of
breath after aspirating a water soluble contrast for
investigation of dysphagia. A Computed Tomography
(CT) of chest was performed and it revealed a right
lower lobe vascular lesion with surrounding
inflammation (Figure 1). A further Computed
Tomography Pulmonary Angiogram (CTPA) was
obtained and confirmed the suspicion of arterio-venous
malformation (AVM) (Figure 2). A multidisciplinary
team was convened and the decision for surgical
resection of the lesion was planned. A pre-operative
CT scan was performed two months after the
diagnosis was made. In contrast to the initial CT scan,
the vascular lesion has surprisingly completely
resolved and only a focal inflammation was left
in-situ.
Figure 1 The above shows sagittal view of non contrast (prior)
and contrast enhanced (posterior) CT scan of the chest. Both
show pulmonary AVM in the right lower lobe
Preferred citation for this article:
Wong et al., 2013, A Case of a Rare Acquired Inflammatory Arterio-venous Malformation with Spontaneous Resolution, International Journal of Clinical
Case Reports, Vol.3, No.17 76-78 (doi: 10.5376/ijccr.2013.03.0017)
Received: 17 Dec., 2013
|
Accepted: 02 Jan., 2014
|
Published: 08 Feb., 2014
Clinical Case Reports, Int’l Journal of